Disseminated Mycobacterium avium complex infection presenting as superior vena cava syndrome in a patient with anti-interferon-gamma autoantibody: a case report.

Disseminated Mycobacterium avium complex infection presenting as superior vena cava syndrome in a patient with anti-interferon-gamma autoantibody: a case report.

Publication date: Nov 03, 2025

Superior vena cava (SVC) syndrome is primarily associated with malignancy, with infectious etiologies being less common. Tuberculosis is the most common infectious cause of SVC syndrome (SVCS). There has been no report of SVCS caused by nontuberculous mycobacteria (NTM). Here, we present a case of SVCS caused by disseminated Mycobacterium intracellulare in a patient who was previously healthy and subsequently tested positive for anti-interferon gamma autoantibodies. A 38-year-old woman with no significant past medical history presented with a 3-month history of fever, progressive dyspnea, productive cough, and weight loss. She also reported a one-year history of ulcerative wounds on her right ankle and chest wall. On examination, she exhibited fever, tachycardia, tachypnea, facial and bilateral upper extremity edema, and cervical lymphadenopathy. Chest computed tomography revealed a 4-cm right paratracheal mass, causing SVC obstruction, and suspicious lytic lesions in the thoracic bones. Radiologic imaging of the right ankle showed an osteolytic lesion. Tissue specimens from lymph node biopsy and ankle wound demonstrated positive staining for acid-fast bacilli. While awaiting culture results, an anti-interferon gamma autoantibody assay was performed and returned positive. Mycobacterial culture subsequently identified M. intracellulare. Empiric therapy for NTM infection was initiated with imipenem and azithromycin. Following species identification, treatment was switched to a combination of azithromycin, rifampin, ethambutol, and levofloxacin. Clinical symptoms and imaging findings gradually resolved following the treatment. Nontuberculous mycobacterial (NTM) disease is a rare cause of superior vena cava syndrome. In cases of disseminated NTM infection, a thorough evaluation for associated underlying conditions, particularly adult-onset immunodeficiency (AOID), linked to anti-IFN-γ autoantibodies, is essential.

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Concepts Keywords
Avium Adult-onset immunodeficiency
Bones Anti-interferon gamma autoantibody
Fast Nontuberculous mycobacteria
Lymphadenopathy
Mycobacteria

Semantics

Type Source Name
disease IDO complex infection
disease MESH superior vena cava syndrome
disease MESH syndrome
disease MESH malignancy
disease MESH Tuberculosis
pathway KEGG Tuberculosis
disease IDO history
disease MESH dyspnea
disease MESH weight loss
disease MESH tachycardia
disease MESH tachypnea
disease MESH edema
disease IDO assay
disease MESH infection
drug DRUGBANK Imipenem
drug DRUGBANK Azithromycin
drug DRUGBANK Rifampicin
drug DRUGBANK Ethambutol
drug DRUGBANK Levofloxacin
disease IDO immunodeficiency
pathway REACTOME Reproduction
disease MESH Infectious Diseases
drug DRUGBANK Coenzyme M
disease IDO blood
disease MESH etiology
disease MESH thrombus
drug DRUGBANK Sulodexide
disease MESH lymphoma
disease MESH lymphadenopathy
disease MESH arthralgia
drug DRUGBANK Ethanol
disease MESH recurrent infections
drug DRUGBANK Tretamine
drug DRUGBANK Oxygen
drug DRUGBANK Medical air
disease MESH anemia
disease MESH leukocytosis
disease MESH thrombocytosis
drug DRUGBANK Alkaline Phosphatase
drug DRUGBANK Dextrose unspecified form
drug DRUGBANK Methyprylon
disease MESH granuloma
drug DRUGBANK Pentaerythritol tetranitrate
drug DRUGBANK Dihydrostreptomycin
disease IDO susceptibility
drug DRUGBANK Amikacin
disease MESH pneumonia
drug DRUGBANK Tigecycline
drug DRUGBANK Clofazimine
drug DRUGBANK Rifabutin
disease MESH AIDS
disease MESH abnormalities
disease IDO intervention
disease MESH emergencies
disease MESH opportunistic infections
disease MESH talaromyces marneffei infection

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